Congenital forearm pseudoarthrosis associated with proximal radius dislocation: Surgical treatment using a single bone forearm.
DOI:
https://doi.org/10.15417/420Keywords:
Congénita, seudoartrosis, niños, antebrazo de un hueso. Congenital, pseudarthrosis, children, one-bone forearm.Abstract
Introducción
La pseudoartrosis congénita de antebrazo es una entidad clínica rara que se asocia a habitualmente Neurofibromatosis tipo 1. La lesión de ambos huesos del antebrazo asociada con luxación de cabeza de radio es extremadamente inusual.
Material y métodos
Se presenta el caso de una niña de 13 años de edad con Neurofibromatosis tipo 1 y pseudoartrosis de ambos huesos del antebrazo asociada a luxación de la cabeza de radio. Se le realizó escisión amplia de la pseudoartrosis y reconstrucción mediante antebrazo de un hueso con placa. La primer cirugía fracasó y requirió una revisión con retiro del implante, injerto óseo autólogo y fijación con enclavado endomedular. Luego de la segunda cirugía, la niña presenta un antebrazo de un hueso estable, con un acortamiento de 7cms. En el último control, 4 años después, la paciente se encuentra asintomática y utiliza el miembro superior con una mínima limitación de la flexo-extensión de muñeca.
Conclusión
La reconstrucción mediante antebrazo de un hueso es una opción razonable para la pseudoartrosis de ambos huesos del antebrazo con luxación de cabeza radial en niños. El procedimiento de salvataje, produce un miembro superior estable, con una función satisfactoria de muñeca y codo.
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References
Aegerter EE. The possible relationship of neurofibromatosis, congenital pseudarthrosis, and fibrous dysplasia. J BoneJointSurg [Am]. 1950;32: 618–626. DOI: https://doi.org/10.2106/00004623-195032030-00016
Crawford AH. Neurofibromatosis in the pediatric patient. Orthop Clin North Am. 1978;9:11–23. DOI: https://doi.org/10.1016/S0030-5898(20)30878-6
Crawford, A H. and Schorry E K..Neurofibromatosis Update. J PediatrOrthop 2006;26:413-423 DOI: https://doi.org/10.1097/01.bpo.0000217719.10728.39
Lee DY, Cho TJ, Lee HR, Lee K et al. Disturbed Osteoblastic Differentiation of Fibrous Hamartoma Cell from Congenital Pseudoarthrosis of the Tibia Associated with Neurofibromatosis Type 1. Clinics in Orthopedic Surgery. 2011;3:230-237. DOI: https://doi.org/10.4055/cios.2011.3.3.230
Cobb N: Neurofibromatosis and pseudarthrosis of the ulna. J Bone Joint Surg 1974; 56 A: 191-4 DOI: https://doi.org/10.2106/00004623-197456010-00024
Richin PF, Kranik A, Van Herpe L, et al. Congenital pseudarthrosis of both bones of the forearm. A case report. J Bone Joint Surg [Am]. 1976; 58:1032–1033. DOI: https://doi.org/10.2106/00004623-197658070-00028
Hadlow V. Congenital pseudarthrosis of the ulna: a case report. Aust NZ J Surg. 1979;49:100–104. DOI: https://doi.org/10.1111/j.1445-2197.1979.tb06449.x
Allieu Y, Meyer ZU, Reckendorf G, et al. Congenital pseudarthrosis of both forearm bones: long-term results of two cases managed by free vascularized fibular graft. J Hand Surg [Am]. 1999;24:604–608. DOI: https://doi.org/10.1053/jhsu.1999.0604
Bayne LG: Congenital pseudartrhosis of the forearm. Hand Clinics 1985;3:457-65. DOI: https://doi.org/10.1016/S0749-0712(21)01375-5
Bell DF. Congenital forearm pseudarthrosis: report of six cases and review of the literature. J PediatrOrthop. 1989;4:438–443. DOI: https://doi.org/10.1097/01241398-198907000-00011
Mathoulin C, Gilbert A, Azze RG. Congenital pseudarthrosis of the forearm: treatment of six cases with vascularized fibular graft and a review of the literature. Microsurgery. 1993;14:252–259. DOI: https://doi.org/10.1002/micr.1920140408
Charles YP, Dimeglio A, Chammas M: Congenital pseudarthrosis of the forearm. Report of two cases and review of the literature. Chir Main 2009;28(1):26-32 DOI: https://doi.org/10.1016/j.main.2008.11.003
Pauletti A, Cervigni F, Castillo J y cols. Injerto de peroné vascularizado en la seudoartrosis congénita. Rev Asoc. Arg. Ortop. yTraumatol. 2000;65(2):97-101.
Ostrowski DM, Eilert RE, Waldstein G. Congenital pseudarthrosis of the ulna: a report of two cases and review of the literature. J PediatrOrthop. 1985;5:463–467. DOI: https://doi.org/10.1097/01241398-198507000-00015
Witoonchart K, Uerpairojkit C, Leechavengvongs S, et al. Congenital pseuarthrosis of the forearm treated by free vascularized fibular graft: a report of three cases and a review of the literature. J Hand Surg [Am]. 1999;24:1045–1055. DOI: https://doi.org/10.1053/jhsu.1999.1045
Bae DS, Waters PM, Sampson CE. Use of free vascularized fibular graft for congenital ulnar pseudarthrosis: surgical decision making in the growing child. J Pediatr Orthop. 2005 Nov-Dec;25(6):755-62. DOI: https://doi.org/10.1097/01.bpo.0000186241.29415.df
Hey-Groves EW. Modern methods of treating fractures, 2da. ed. Bristol: John Wrisght& Sons; 1921 p.320.
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